Session I: Caspases                                             Sunday April 2nd

 

BCR-INDUCED APOPTOSIS IS INITIATED BY A zVAD-INSENSITIVE PROTEASE WHICH IS UNDER DIRECT CONTROL OF CD40

Eric ElderingH, Susanne M.A. Lens*H, Bianca F.A. den Drijver*, Ingrid A.M. Derks, Jannie BorstI, Marinus H.J van Oers' and René A.W. van Lier*H

Depts. of *Immunobiology, CLB, HClinical Immunology Laboratory, AMC, ICellular Biochemistry, NCI, and 'Hematology, AMC, Amsterdam, The Netherlands

 B-cell antigen receptor (BCR)-induced apoptosis is accompanied by cleavage of caspase (casp) 3. We have shown that in the B-cell line Ramos it takes place independently from the adaptor protein FADD and is not inhibited by overexpression of FLIP. Thus, the initial stages of BCR-mediated apoptosis differ strikingly from the CD95-pathway. In addition, after BCR cross-linking, conversion of casp-3 from p32 to p20 can not be blocked by the broad spectrum caspase inhibitor z-VAD-fmk, while processing of the related executioner casp-7 can be blocked completely. In contrast to z-VAD-fmk, ligation of CD40 prevents BCR-induced casp-3 processing and apoptosis completely, even when this signal is delivered 12 hours after cross-linking of the BCR. Finally, triggering of the BCR induces the release of cytochrome C from mitochondria in a z-VAD-fmk insensitive but CD40-regulated fashion. We conclude that the BCR can couple to the classical caspase cascade via a specific proteolytic pathway which is under direct control of T-helper signals. Calpain (Ruiz-Vela etal., EMBO 18, 4988, ’99) and caspase-2 (Chen etal., J Imm 163, 2483, ’99) have recently been proposed as mediators of BCR-induced apoptosis, but no direct comparison of BCR- vs. CD95-triggering involving these proteases has yet been made. Our current efforts include expression of caspase-2 constructs in Ramos with which we will be able to further dissect the BCR- and CD95-pathways.

 

A regulatory role for Apaf 1 in Caspase 9 function

Srinivasa M. Srinivasula, Ayman saleh, Manzoor Ahmad, Teresa Fernandes-Alnemri, Emad S. Alnemri.

Center for Apoptosis Research and Department of Microbiology and Immunology, Kimmel Cancer Institute, Thomas Jefferson University, Philadelphia, PA 19107, USA

 

Caspases play a fundamental role in the initiation and execution of apoptosis. Though Apaf 1 is required for oligomerization and autocatalytic activation of caspase 9, its role in the caspase cascade after processing of caspase 9 is not yet clear. Using pure recombinant Apaf 1, completely processed and unprocessed caspase 9 and procaspase 3 we provide evidence that Apaf 1 is the only factor required for the activation of caspase 9 and caspase 3. Apaf 1 also positively regulates the enzymatic activity of caspase 9 by forming a holoenzyme complex with fully processed or unprocessed caspase 9. At physiological concentrations both completely and unprocessed caspase 9 have no enzymatic activity , but express equivalent enzymatic activity towards procaspase 3 when incubated with Apaf 1, cytochrome c and dATP. In contrast completely processed prodomain mutant (R56A) of caspase 9, which can not bind to CARD domain of Apaf 1, remains enzymatically inactive towards procaspase 3 even inpresence of Apaf 1, cytochrome c and dATP. These data suggests that fully processed caspase 9 requires binding to Apaf 1 for expression of its optimal activity. We believe that such a regulation of processed caspase 9 activity by Apaf 1 or any other isoforms of Apaf 1 that may exist in cell plays an important role in cell differentiation and death.

 

Session I: Caspases                                             Sunday April 2nd

 

DRADD is a nuclear-localized death domain adaptor protein that binds caspase-9 and promotes apoptosis

Colin Adrain, Mary T. Harte, Helen Egan, Liam Carlin, Elizabeth A. Slee and Seamus J. Martin

Molecular Cell Biology Laboratory, Department of Genetics, The Smurfit Institute, Trinity College, Dublin 2, Ireland

Apoptosis is coordinated by a family of cysteine proteases, the caspases, that dismantle the cell by cleaving a subset of cellular proteins after aspartic acid residues. Caspases are frequently activated at the onset of apoptosis by recruitment to adaptor proteins that promote aggregation of particular caspases and facilitate their processing. Caspase-9 is activated in the cytosol through recruitment to Apaf-1, a human homologue of the C elegans CED-4 protein. To identify other caspase-9-binding proteins, we performed a two-hybrid screen with the N-terminal caspase recruitment domain (CARD) region of human caspase-9. This screen yielded multiple copies of a protein which we have called DRADD. DRADD possesses a C-terminal death domain as well as a caspase-recruitment domain (CARD) that is specific for caspase-9. Whereas transient overexpression of full-length DRADD did not promote apoptosis, truncations of this protein containing the CARD domain did so. Interestingly, in contrast to most caspase adaptor proteins described to date, DRADD expression is strongly localized to the nucleus. DRADD may be involved in initiating caspase activation in response to stimuli that provoke nuclear damage.

 

Apoptin induces apoptosis specifically in human tumor cells: studies on its mechanism

Astrid A.A.M. Danen-van Oorschot1,2, Arend van Zon1, Maud C.M.J. Seelen2 and Mathieu H.M. Noteborn1,2

1 Molecular Cell B

2 Leadd BV, PO Box 9503, 2300 RA, Leiden, The Netherlands

 Apoptin, a protein derived from chicken anemia virus (CAV), induces apoptosis in various human transformed or tumor cell lines, even those lacking p53 or overexpressing Bcl-2. Interestingly, apoptin does not induce apoptosis in any of the human normal diploid cells tested to date. Elucidation of the molecular mechanism of apoptin-induced apoptosis is important for its potential use as an anti-tumor agent. Moreover, it may shed light on the characteristics underlying the transformed state of a cell, which possibly provides new drug targets for cancer therapy. Experiments with inhibitors of specific caspases indicate that activation of upstream caspases is not essential, but downstream caspases do seem to be required for apoptin-induced apoptosis. In immunofluorescence assays, active caspase-3 could be detected in cells undergoing apoptin-induced apoptosis. In transformed or tumor cells apoptin is mainly present in the nucleus, whereas in normal diploid cells apoptin is predominantly located in the cytoplasm. Mutations preventing nuclear localization of apoptin also reduce its apoptotic activity. However, a fusion protein of apoptin and a strong NLS results in nuclear localization in normal diploid cells, but not in induction of apoptosis. These observations indicate that nuclear localization is important, but not sufficient for apoptin-induced apoptosis.

 

Session I: Caspases                                             Sunday April 2nd

 

Two Cell Death Pathways leading to Necrosis and Apoptosis : Differential Role of Caspases and Mitochondria

Geert van Loo, Geertrui Denecker, Margino Steemans, Dominique Vercammen, Wim Declercq, Walter Fiers, Johan Grootten & Peter Vandenabeele

Molecular Signalling and Cell Death Unit, Department of Molecular Biology, Flemish Interuniversity Institute for Biotechnology (VIB)

University of Gent (RUG), Ledeganckstraat 35, B-9000 Gent (Belgium)

 Apoptosis and necrosis are often described as two distinct ways of cell death. However, most comparative studies are based on the use of different cell lines or unrelated stimuli. In order to compare the signalling pathways of both types of cell death in the same cells initiated by death domain receptors, murine L929sA fibrosarcoma cells were transfected with the human Fas receptor (CD95). The cells treated with agonistic anti-Fas exhibited a clear apoptotic phenotype, while TNF treatment led to necrosis. We studied the release of mitochondrial factors in both types of cell death and the influence of Bcl-2. We will also provide evidence for a protective role of caspase-8 in the necrotic process. The presence of caspase-inhibitors blocks Fas-induced apoptosis, but later on the cells die by necrosis. The necrotic process is not accompanied with activation of caspases and is prevented by the addition of oxygen radical scavengers and serine protease inhibitors. This indicates that TNF-R1- and Fas-initiated necrosis occur independent of the FADD-procaspase-8 effector axis. It also implies that in the absence of caspase activation another cell death pathway than apoptosis may be initiated from the death domain receptors or death domain containing associated proteins, in which serine proteases and generation of mitochondrial reactive oxygen intermediates are implicated.

 The Viral nucleocapsid protein of the transmissible gastroenteritis coronavirus, TGEV, is a target for caspase -6 and -7

J.-F. Eléouët1, E. Slee2,4, F. Saurini1, N. Castagné1, D. Poncet1, C. Garrido3, E. Solary3, and S. J. Martin2,4.

1VIM, INRA, 78352 Jouy-en-Josas, France; 2Molecular Cell Biology Laboratory, National University of Ireland, Maynooth, Co. Kildare, Ireland; 3U.F.R. Médecine et Pharmacie, INSERM U517, 7 Boulevard Jeanne d'Arc 21000 Dijon, France. 4Present address: Division of Molecular and Cell Biology, The Smurfit Institute of Genetics, Trinity College, Dublin 2, Ireland

 Transmissible gastroenteritis coronavirus (TGEV), which causes acute and fatal diarrhea in newborn pigglets, exerts much of its cytotopathic effects through induction of apoptosis of its host cell. The present study shows that infection of the human rectal tumor cell line HRT118, modified to express the porcine aminopeptidase N which is the receptor for TGEV, results in the activation of caspases -3, -6, -7, -8, and -9 and cleavage of the caspase substrates eIF4GI, gelsolin and a-fodrin in host cells. Interestingly, apoptosis of TGEV-infected HRT18 cells was associated with proteolysis of the TGEV nucleocapsid (N) protein. N protein cleavage, that was inhibited by cell permeable caspase inhibitors, was reproduced in vitro by incubating the protein with either caspase-6 or caspase-7. The site of N protein cleavage by caspases was mapped to VVPD359Ø. These results indicate that cells undergoing cell death upon viral infection can alter viral structural proteins through caspase-mediated proteolysis.

 

Session II: Mitochondria and cytotoxic drugs           Sunday April 2nd

 

Regulation of caspase-dependent but not caspase-indipendent cell death by the multidrug resistance protein, P-glycoprotein

Ricky W. Johnstone, Astrid A. Ruefli, Kelly M. Tainton and Mark J. Smyth.

The Austin Research Institute, Heidelberg, Victoria, Australia

 Multidrug resistance (MDR) is characterized by the expression of P-glycoprotein (P-gp), a 170kD ATP-dependent drug efflux protein. As well as effluxing xenotoxins, functional P-gp can confer resistance to caspase-dependent apoptosis induced by a range of different stimuli including Fas ligand, TNF, UV irradiation and serum starvation. However, P-gp positive cells remain sensitive to caspase-indipendent death induced by cytotoxic T cell granule proteins, perforin and granzyme B. It is therefore possible that agents that induce cell death in a caspase-indipendent manner might circumvent P-gp-mediated MDR. We now evidence that Hexamethylene bisacetamide (HMBA) can induce equivalent caspase-indipendent cell death in both P-gp positive and negative cell lines. The HMBA-induced death pathway is marked by release of cytochrome c from the mitochondria and reduction of Bcl-2 protein levels. In addition, functional P-gp can specifically inhibit the activation of caspases-8 and –3, caspase-9 remains unaffected. These studies greatly enhance our understanding of the molecular cell death events that can be regulated by functional P-gp and highlight the potential clinical use of drugs that function via a caspase-indipendent pathway for the treatment of MDR tumors.

 

Oxidation of a Critical Thiol Residue of the Adenine Nucleotide Translocator Enforces Bcl-2-Independent Permeability Transition Pore Opening and Apoptosis

Paola Costantini1, Anne-Sophie Belzacq2, Helena L.A. Vieira1, Nathanael Larochette1, Manuel de Pablo1, Naoufal Zamzami1, Santos A. Susin1, Catherine Brenner2, and Guido Kroemer1

1 Centre National de la Recherche Scientifique, ERS 1984, 19 rue Guy Môquet, F-94801 Villejuif, France; 2 Centre National de la Recherche Scientifique, UPRES-A6022, Université Technologique de Compiègne, F-60205 Compiègne, France

 Mitochondrial membrane permeabilization is a critical event in the process leading to physiological or chemotherapy-induced apoptosis. This permeabilization event is at least in part under the control of the permeability transition pore complex (PTPC), which interacts with oncoproteins from the Bcl-2 family as well as with tumor suppressor proteins from the Bax family, which inhibit or facilitate membrane permeabilization, respectively. Here we show that thiol crosslinking agents including diamide, dithiodipyridine (DTDP), or bis-maleimido-hexane (BMH) can act on the adenine nucleotide translocator (ANT), one of the proteins within the PTPC. ANT alone reconstituted into artificial lipid bilayers suffices to confer a membrane permeabilization response to thiol crosslinking agents. Diamide, DTDP, and BMH but not tert-butylhydroperoxide or arsenite cause the oxidation of a critical cysteine residue (Cys 56) of ANT. Thiol modification within ANT is observed in intact cells, isolated mitochondria, and purified ANT. Recombinant Bcl-2 fails to prevent thiol modification of ANT. Concomitantly, a series of different thiol crosslinking agents (diamide, DTDP, and BMH, phenylarsine oxide) but not tert-butylhydroperoxide or arsenite induce mitochondrial membrane permeabilization and cell death irrespective of the expression level of Bcl-2. These data indicate that thiol crosslinkers cause a covalent modification of ANT which, beyond any control by Bcl-2, leads to mitochondrial membrane permeabilization and cell death.

 

Session II: Mitochondria and cytotoxic drugs           Sunday April 2nd

 

Biochemical differences in apoptosis induced by CD95 ligation or thymidilate-synthase inhibition

Cristina Muñoz-Pinedo and Abelardo López-Rívas

Instituto de Parasitología y Biomedicina, CSIC, Granada, Spain

 Drugs that inhibit dTTP synthesis induce apoptosis in a wide range of cell types, and are currently used in chemotherapy. Despite of this, the mechanism of induction of cell death is not fully understood. Previous results of our lab indicate that, in hematopoietic cells, p53 accumulation or CD95‑CD95L are not implicated in death response to the thymidilate‑syntase inhibitor 5'fluor, 2'deoxyuridine (FUdR, Floxuridine). In this report, we have examined the mechanism of apoptosis induced either by FUdR or CD95‑triggering in hematopoietic U937 cells. Caspase-8, a classically death receptor‑associated caspase, was activated by both types of death inducers. Neverthless, inhibition of caspases‑8 with a specific peptide caused only a slight delay in FUdR‑induced death, while completely inhibited CD95‑induced apoptosis. Furthermore, inhibition of caspases‑8 inhibited cytochrome C release only when celIs were treated with anti‑CD95, but not with FUdR. Requirement of ATP was also addressed. While apoptotic death induced by FUdR was reduced by depletion of ATP, anti‑CD95‑induced apoptosis was not inhibited. Studies of mitochondrial depolarization and cytochrome C release showed that ATP was required in FUdR‑induced apoptosis at a pre‑mitochondrial or mitochondrial level.

 

GRANZYME B INDUCED APOPTOSIS IS REGULATED BY PRO- AND ANTI-APOPTOTIC MEMBERS OF THE BCL-2 FAMILY

Vivien R.Sutton, David Huang*, Michael Cancilla*, Ricky Johnstone, Karin Sedelies, Astrid Ruefli, Joanne Davis and Joseph Trapani.

The Austin Research Institute, Heidelberg, Vic., 3084 and * The Walter and Eliza Hall Institute of Medical Research, Royal Melbourne Hospital, Vic., 3050

 We have previously shown that Bcl-2 overexpression in mouse FDC-P1 or human Jurkat cells blocks the apoptotic changes induced by GrB, including mitochondrial depolarisation, cytochrome c release, DNA fragmentation, and plasma membrane damage. We now report that sensitivity to GrB was restored by co-expression of the pro-apoptotic bcl-2-related protein BID, whereas the same cells remained protected from growth factor deprivation or treatment with staurosporine. BID cleavage was observed only in response to GrB, but not to other apoptotic stimuli. Time-course studies demonstrated that cleavage of either overexpressed or endogenous BID was extremely rapid (within 2 minutes) and was not slowed by over-expression of Bcl-2. We next examined the effect of introducing mutations in the cleavage sites of BID. BID in which the GrB cleavage site (D75) was mutated to Ala was unable to restore GrB-mediated apoptosis to Bcl-2 expressing cells. However, mutation of the caspase 8 site (D59) did not prevent GrB-induced BID cleavage or apoptosis. In untransfected Jurkat cells, inhibition of caspases with z-VAD-fmk abrogated GrB -induced nuclear damage, whereas BID cleavage and cytochrome c release were still observed, and the cells failed to survive in clonogenic growth assays. Collectively, our findings indicate that Bcl-2 controls a key upstream event in GrB-mediated cell death, and that GrB-induced cell death (both caspase-dependent and -independent) is initiated by direct BID cleavage by GrB. Consequently, GrB-induced mitochondrial events do not require active caspases.

 

Session II: Mitochondria and cytotoxic drugs           Sunday April 2nd

 

GD3 GANGLIOSIDE INDUCES APOPTOSIS VIA DIRECT MITOCHONDRIAL DAMAGE IN A BCL-2 CONTROLLED FASHION

M.R. Rippo*, F. Malisan*, L. Ravagnan#, B. Tomassini*, I. Condo'*, P. Costantini#, S.A. Susin#, A. Rufini*, G. Kroemer# and R. Testi*

*Laboratory of Signal Transduction, Department of Experimental Medicine and Biochemical Sciences, University of Rome "Tor Vergata" and # Centre National de la Recherche Scientifique, UPR 420, Villejuif, France

 GD3 ganglioside is an intracellular effector of Fas-induced apoptotic signal mediated by ceramide. GD3, indeed, accumulates in hematopoietic cells upon Fas and ceramide stimulation and blocking the GD3 neosynthesis strongly delays the Fas- or ceramide- induced apoptotic program. Moreover, exogenous GD3 can directly induce DNA fragmentation and apoptosis. In hematopoietic cells, GD3 induces a massive mitochondrial damage. Here we show that on isolated mitochondria GD3, but not other gangliosides, induces mitochondrial swelling, external mitochondrial membrane disruption, and release of apoptogenic factors such as cytochrome c and AIF (Apoptosis Inducing Factor). All these events are prevented by treatment with cyclosporine A, suggesting that GD3 induces permeability transition (PT) pore opening. Supernatants of GD3 treated mitochondria, but not GD3 alone, induce DNA fragmentation of isolated nuclei, indicating that the target for GD3 is on mitochondria. Accordingly, suppression of GD3 synthase (ST8) expression in intact cells substantially prevents ceramide-induced DYm dissipation, indicating that endogenously synthesized GD3 induces mitochondrial changes in vivo. Moreover enforced expression of Bcl-2 prevents GD3-induced mitochondrial changes and apoptosis. All these results show that mitochondria are the key destination for apoptogenic GD3 along the lipid pathway to programmed cell death.

 

Two Distinct Pathways Leading to Nuclear Apoptosis

Luigi Ravagnan 1, Santos A. Susin 1, Eric Daugas 1, 2, Kumiko Samejima 3, Naoufal Zamzami 1, Markus Loeffler 1, Paola Costantini 1, Karine F. Ferri 1, Theano Irinopoulo 4, Marie-Christine Prévost 5, William C. Earnshaw 3, and Guido Kroemer1

1 Centre National de la Recherche Scientifique, ERS 1984, 19 rue Guy Môquet, F-94801 Villejuif, France; 2 Assistance Publique - Hôpitaux de Paris, Service de Néphrologie B, Hôpital Tenon, 20 rue de la Chine, F-75020, France; 3 University of Edinburgh, Institute for Cellular and Molecular Biology, Edinburgh EH93JR, Midlothian, Scotland; 4 INSERM U430, Hôpital Broussais, 14 rue Didot; F-75014 Paris, France; 5 Unité d'Oncologie Virale, Institut Pasteur, 28 rue du Dr. Roux, F-75724 Paris cedex 15, France

 Apaf-1-/- or caspase-3-/- cells treated with staurosporine (STS) manifest apoptosis-associated alterations including the translocation of AIF from mitochondria to nuclei, large scale DNA fragmentation and initial chromatin condensation (stage 1). However, when compared to normal control cells, Apaf-1-/- or caspase-3-/- cells fail to exhibit oligonucleosomal chromatin digestion and a more advanced pattern of chromatin condensation (stage 2). Microinjection of such cells with recombinant AIF only causes peripheral chromatin condensation, whereas microinjection with activated caspase-3 or its down-stream target CAD causes a more pronounced type of chromatin condensation. This observation has been confirmed in a cell free system. When added to purified HeLa nuclei, AIF causes stage-1 chromatin condensation and large-scale DNA fragmentation, whereas CAD induces stage-2 chromatin condensation and oligonucleosomal DNA degradation. To suppress the chromatin condensation-inducing activity of cytoplasmic extracts from cells undergoing apoptosis, both CAD and AIF must be neutralized concomitantly. As a result, at least two redundant parallel pathways may lead to chromatin processing during apoptosis. One of these pathways involves caspases, ICAD, as well as CAD, and leads to oligonucleosomal DNA fragmentation and advanced chromatin condensation. The other pathway, caspase-independent, involves AIF and leads to large-scale DNA fragmentation and peripheral chromatin condensation.

 

Session II: Mitochondria and cytotoxic drugs          Sunday April 2nd

 

Differential role of caspase 8 and Bid cleavage during CD95- and anticancer drug induced caspase activation

A. Stepczynska, I. Engels, C. Stroh, C. Belka*, S. Wesselborg and K. Schulze-Osthoff

Division of Immunology and Cell Bilogy, University of Muenster, Germany

* Department of Radiation Oncology, University of Tuebingen, Germany

 Multiple interconnected pathways are involved in CD95- and anticancer drug-induced apoptosis. One common feature for the receptor-dependent and -independent pathways to apoptosis is the activation of the executioner caspase 3. Both pathways can be differentiated based on caspase 8 or caspase 9 requirement for caspase 3 activation. To analyze the relative position of caspases 8, 9, 6, and 3 in the caspase cascade of CD95- and anticancer drug-induced apoptosis we utilized caspase 8 deficient, and BclXl or caspase 9 dominant negative (9DN) Jurkat cell line. Although caspase 8 has been previously reported to be dispensable for death receptor-independent apoptosis, we observed the activation of caspase 8 in response to etoposide or staurosporine. In addition, we found that Bid, known as caspase 8 substrate, is also activated by anticancer drugs in the presence or absence of caspase 8. Caspases 9, 6, and 3 activation were inhibited in Jurkat-BclXL and ñ9DN cell lines stimulated with anticancer drugs. Interestingly, caspase 8 and Bid activation were also inhibited in these cell lines indicating that caspase 8 and Bid activation occur downstream of mitochondria in anticancer drug mediated apoptosis. We conclude that caspase 8 plays a role of an executioner caspase in anticancer drug induced apoptosis in contrast to CD95- induced apoptosis. We propose that Bid not only constitutes a link between receptor dependent and independent pathways to apoptosis but also enables an amplification loop for the execution of the anticancer drug induced apoptosis.

 

Session III: Signaling                                  Sunday April 2nd

 

Activation of the Caspase Cascade and the Effect of Ras in Detachment Induced Apoptosis

M. Rytömaa and J. Downward

Signal Transduction Laboratory, Imperial Cancer Research Fund, 44 Lincoln's Inn Fields, London WC2A 3PX, U.K

 Epithelial and endothelial cells undergo apoptosis upon detachment from the matrix, a phenomenon called anoikis. It is known that the activated Ras is able to protect cells from anoikis through its downstream effectors PI 3-kinase and Akt/PKB. The pathways involved in anoikis and the way Ras effectors work are not yet clear and this work gives some new insight to this area. We have shown that detachment of MDCK cells from the matrix leads to the activation of caspase-8 and downstream effector caspases. Interestingly, in MDCK cells stably expressing V12 Ras, v-Akt, or dominant negative FADD, no detachment-induced caspase-8 activation or DNA fragmentation were detected. The activation of caspases can be blocked by inhibitor peptides, such as z-VAD, which also protects cells from anoikis. Detachment of MDCK cells from matrix also leads to release of cytochrome c form mitochondria to cytoplasm and this is blocked by V12 Ras as well as v-Akt. Importantly, the release of cytochrome c is caspase dependent since z-VAD is able to prevent it. However, an other downstream effector of Ras, Raf, is not able to block cytochrome c release even through it is blocking detachment induced apoptosis.

Regulation of Cell Survival by the MAPK-activated kinase, RSK1 and the Phosphoinositide-Dependent Kinase, PDK1

1 Bryan A. Ballif, 1,2 Akiko Shimamura, 1 Stephanie A. Richards, John Blenis

1 Department of Cell Biology, Harvard Medical School, Boston, Massachusetts, 02115, USA  

2 Department of Pediatric Hematology/Oncology, Dana Farber Cancer Institute, Boston, Massachusetts 02115, USA

 Aberrant cell death or inappropriate cell survival are primary causes in diseases as diverse as neoplastic transformation, autoimmunity, and neurodegeneration. Over the last few years a handful of signaling molecules have been identified as transducers of growth-factor-regulated cell survival signals. Both the PI3-kinase/Akt and the MEK/MAPK signaling casettes constitute key regulatory pathways promoting cell survival. Whereas the molecular basis of Akt’s pro-survival signal is multifactorial and a number of downstream effectors have been identified, the downstream effectors of the mammalian MEK/MAPK cell survival signal have not been previously described. These studies identify a pro-survival role for a downstream target of the MEK/MAPK signaling pathway, RSK1. Experiments in vitro and in vivo demonstrate that RSK1 directly phosphorylates BAD at the serine residues critical for abrogation of BAD’s pro-apoptotic function. A novel constitutively active RSK1 mutant confers constitutive BAD phosphorylation and protection from IL-3 withdrawal-induced cell death. Conversely, kinase-inactive RSK1 mutants antagonize both BAD phosphorylation and the MEK survival signal. BAD mutations that prevent phosphorylation by RSK1 also inhibit RSK1-mediated cell survival. Additionally, we have identified a novel inhibitor of Phosphoinositide-Dependent Kinase-1 (PDK-1). PDK1 activates a growing number of kinases in the AGC kinase superfamily including PKA, PKC, Akt, RSK, SGK, and S6 kinases-1 and -2. PDK-1 is thus positioned at the apex of numerous kinase cascades governing multiple aspects of normal and aberrant cellular functions including cell survival. Consistent with the requirement for PDK1 in activating the pro-survival, BAD kinases Akt, RSK and PKA, pharmacological inhibition of PDK1 eliminated IL-3 dependent BAD phosphorylation and led to cell death in IL-3-dependent 32D cells.

 

Session III: Signaling                                  Sunday April 2nd

 

A nuclear tyrosine phosphorylation circuit: c-Jun as an activator and substrate of c-Abl and JNK

Daniela Barilá1, Raffaella Mangano, Stefania Gonfloni, Marina Moro, Jana Kretzschmar, Dirk Bohmann, Roberto Testi2 and Giulio Superti-Furga

European Molecular Biology Laboratory Meyerhofstrasse 1 69117 Heidelberg, Germany. 1present address: University of Rome “Tor Vergata” Department of Experimental Medicine and Biochemical Sciences” Via di Tor Vergata 135 00133 Rome, Italy. 2University of Rome “Tor Vergata” Department of Experimental Medicine and Biochemical Sciences” Via di Tor Vergata 135 00133 Rome, Italy

 The nuclear function of the c-Abl tyrosine kinase is not well understood. In order to identify nuclear substrates of Abl, we constructed a constitutively active and nuclear form of the protein. The expression of a constitutively active form of Abl in the nucleus is highly toxic for the cell. We found that active nuclear Abl efficiently phosphorylates c-Jun, a transcription factor not previously known to be tyrosine phosphorylated. After phosphorylation of c-Jun by Abl on tyrosine 170, both proteins interacted via the SH2 domain of Abl. Surprisingly, elevated levels of c-Jun activated nuclear Abl, resulting in activation of the JNK serine/threonine kinase. This phosphorylation circuit generates nuclear tyrosine phosphorylation and represents a reversal of previously known signalling models. We are currently investigating the structural requirements of Abl and the possible role of Jun phosphorylation in the induction of cell death.

 

Chemokine receptor homo- and heterodimerization as a cellular mechanism to increase sensitivity and dynamic range of chemotaxis  

Antonio J. Vila-Coro, Mario Mellado, Ana Martín de Ana, Carlos Martínez-A. and José Miguel Rodríguez-Frade

Departamento de Imunologìa y Oncologìa. Centro Nacional de Biotecnologìa

 The role of dimerization in G protein-coupled receptor signaling has recently been demonstrated. Two different families of these receptors appear to follow distinct strategies during the formation of this supramolecular complex. The GABA receptor is composed of two subunits that require close association to transmit the GABA signal within the neuron, allowing activation of potassium channels. The chemokine receptor undergoes a ligand-mediated homodimerization process that is required for Ca2+ flux and chemotaxis. Here we show that, in the chemokine response, heterodimerization is also permitted between given receptor pairs, specifically between the CCR2 and the CCR5 receptors, but not between the CCR2 and the CXCR4 receptors. This heterodimerization results in recruitment of the signaling complex associated to both receptors, as measured by association of JAK tyrosine kinases and STAT transcription factors to the receptor complex. This has functional consequences, since calcium responses are triggered in the presence of MCP-1 and RANTES at concentrations 10-100 fold lower than the threshold for each chemokine when added individually. In addition, expression of a CCR2 death receptor with the Tyr139Phe mutation, which impairs CCR2 responses, blocks responses triggered through the CCR5 receptor. These results may be relevant for in vivo chemotaxis under limiting chemokine concentrations. They also show the structural constraints on chemokine receptors for homo- and heterodimer formation in the presence of the appropriate ligands, and the implications of dimer formation for increasing the sensitivity and dynamic range of the chemokine response. The role of dimerization in G protein-coupled receptor signaling has recently been demonstrated. Two different families of these receptors appear to follow distinct strategies during the formation of this supramolecular complex.

 

Session III: Signaling                                 Sunday April 2nd

 

The GABA receptor is composed of two subunits that require close association to transmit the GABA signal within the neuron, allowing activation of potassium channels. The chemokine receptor undergoes a ligand-mediated homodimerization process that is required for Ca2+ flux and chemotaxis. Here we show that, in the chemokine response, heterodimerization is also permitted between given receptor pairs, specifically between the CCR2 and the CCR5 receptors, but not between the CCR2 and the CXCR4 receptors. This heterodimerization results in recruitment of the signaling complex associated to both receptors, as measured by association of JAK tyrosine kinases and STAT transcription factors to the receptor complex. This has functional consequences, since calcium responses are triggered in the presence of MCP-1 and RANTES at concentrations 10-100 fold lower than the threshold for each chemokine when added individually. In addition, expression of a CCR2 death receptor with the Tyr139Phe mutation, which impairs CCR2 responses, blocks responses triggered through the CCR5 receptor. These results may be relevant for in vivo chemotaxis under limiting chemokine concentrations. They also show the structural constraints on chemokine receptors for homo- and heterodimer formation in the presence of the appropriate ligands, and the implications of dimer formation for increasing the sensitivity and dynamic range of the chemokine response.

 

Session IV: Neurology                                             Sunday April 2nd

 

Fas/CD95/APO-1 can Function as a DeathReceptor for Neuronal Cells in Vitro and in Vivoand is Upregulated Following Cerebral Hypoxic-Ischemic Injury to theDeveloping Rat Brain

Ursula Felderhoff-Mueser1,2, Deanna L. Taylor1, KirstyGreenwood1, Mary Kozma1, DietgerStibenz3, Umesh C. Joashi1, A. David Edwards1 and Huseyin Mehmet1

1Weston Laboratory,Division of Paediatrics, Obstetrics and Gynaecology, Imperial College ofScience, Technology and Medicine, Hammersmith Hospital, Du Cane Road,London W12 0NN, UK and 2Clinic for Neonatology and 3Institutfür Diagnostikforschung (IDF) der FU Charité Children´s Hospital,Virchow Campus, Humboldt University 13353 Berlin, Germany

 

Fas/CD95/Apo-1 is a cell surface receptor that transduces death signalsfollowing activation and has been implicated in triggering apoptosis ininfected or damaged cells in disease states. Apoptosis is a major mechanismof neuronal loss following hypoxic-ischaemic injury to the developing brain, although the role of Fas in thisprocess has not been studied in detail. In the present study, we haveinvestigated the expression and function of Fas in neuronal cells invitro and in vivo. Fas was found to be expressed in the 14 day old rat brain, with strongestexpression in the cortex, hippocampus and cerebellum. Cross-linking of Fasinduced neuronal apoptosis both in neuronal PC12 cells in culture and following intracerebral injection in vivo, indicating that neuronal Fas was functional as a death receptor. Fasinduced death was caspase dependent in primary neuronal cultures and wasblocked by the selective caspase 8 inhibitor IETD. Finally, cerebral hypoxia ischaemia resulted in a strong lateralised upregulation of Fas inthe hippocampus, that peaked six to twelve hours after the insult and wasgreater on the side of injury. These results suggest that Fas may beinvolved in neuronal apoptosis following hypoxic-ischaemic injury to the developing brain.

 

Differential Effects of Bcl-2, Caspase Inhibition and PARP Deletion on Survival of Intracerebral Neuronal Transplants

Marcel Leist 1, Gabriele Schierle 2, Oskar Hansson 2, Pierluigi Nicotera 1, Patrik Brundin 2

1Molecular Toxicology, Faculty of Biology, Konstanz University, D-78457 Konstanz, Germany. 2Section for Neuronal Survival, Wallenberg Neuroscience Center, Lund University, S-22362 Lund, Sweden

 

The causes of death of transplanted neurons are not known in detail, but apoptotic mechanisms are likely to play a role. We examined whether overexpression of Bcl-2, inhibition of caspases or deletion of poly-(ADP-ribose) polymerase (PARP) may enhance the survival of grafted neurons. Initially, cells were prepared from mice overexpressing human Bcl-2 or lacking PARP, or from their wild-type littermates. The bcl-2 transgene resulted in protection of neurons from staurosporine exposure or growth factor withdrawal in vitro. To model pretransplantation stress more closely in vitro, we stored dissociated cells for eight hours in the same type of medium as used for intracerebral transplantation. This resulted in massive cell death as quantified by lactate dehydrogenase-release, and increased DNA-fragmentation. This cell loss was strongly reduced by different caspase inhibitors, but neither Bcl-2 nor PARP had any significant protective effect. Finally, cells from rats, mice or human embryos were grafted into the striatum of hemiparkinsonian rats. Caspase inhibition significantly increased neuronal survival, functional recovery and fibre outgrowth after several weeks. Bcl-2 or PARP had no effect in murine grafted neurons. Cell death in neuronal transplants seems to involve PARP-independent apoptotic mechanisms that involve the activation of caspases, but that bypass negative regulation by Bcl-2.

 

Session IV: Neurology                                  Sunday April 2nd

 

APOPTOSIS CONTRIBUTES TO NEURONAL LOST FOLLOWING SPINAL CORD TRAUMA

Deana Demjen, Ana Martin-Villalba, Susanne Kleber, Manfred Zimmermann, Johannes Schenkel

Institute of Physiology and Pathophysiology, University of Heidelberg, Germany

 

The spinal cord is made of the motor and sensory pathways between brain and body. Injury of the spinal cord results in a disruption of these pathways and in permanent dissability of a typically young patient. There is growing evidence that neuronal death following spinal cord trauma may be in part an apoptotic event. We investigated the presence of apoptotic cells in an animal model of spinal cord trauma. Numerous TUNEL-positive cells appeared both adjacent to and distant from the injured site 24 hours after transection of the spinal cord. TUNEL-positive cells were still present but to a lesser extent three days after the injury. Apoptosis was accompanied by increased expression of the transcription factor c-Jun and of the death-ligands TNF and CD95-Ligand. Further examination of gld mice (expressing a mutated CD95-Ligand protein) and TNF-knockout mice are currently being undertaken. Our finding helps unraveling the mechanism underlying neuronal lost following spinal cord injury.

 

SYNERGISTIC INHIBITION OF CD95 LIGAND AND TNF ATTENUATES BRAIN DAMAGE IN STROKE

Ana Martin-Villalba1,2, Johannes Schenkel1, Susanne Kleber1, Johannes Vogel1, Henning Walczak2, Heinz Krestel3, Michael Hahne4, Peter H. Krammer2

1 Department of Physiology, University of Heidelberg, Heidelberg 2Tumorimmunology Programm, German Cancer Research Center, Heidelberg 3 Departments of Molecular Neuroscience and Cell Physiology, Max Planck Institute for medical research, Heidelberg, 4Department of immunology, National Center of Biotechnology, Madrid

 

Stroke is the most common cause of death in the western world and still its therapeutical possibilities remain low. There is evidence that the death-inducing ligands TNF and CD95-Ligand are involved in triggering ischemic neuronal death. We examined the contribution to brain damage of these ligands in a rodent model of stroke. In the present study we show that mice deficient in TNF (tnf -/-) and in functional CD95L (gld) are protected against brain ischemia. This protection is greatly enhanced in mice lacking both death ligands    (gld/tnf -/-). In wild-type mice therapeutic application of antibodies against TNF and CD95L diminished infarct volumes and significantly improved survival of the animals. Most importantly, intact functionality of rescued neurons in vivo was demonstrated by the almost normal locomotor performance exhibited by treated animals. Thus, neutralization of CD95L and TNF may support the treatment of stroke.

 

Session IV: Neurology                                             Sunday April 2nd

 

ATP-control of neuronal apoptosis triggered by microtubule breakdown

C. Volbracht, M. Leist, P. Nicotera

 Department of Molecular Toxicology, University of Konstanz, D-78457 Konstanz, Germany

 

Early loss of neurites followed by delayed damage of neuronal somata is a feature of several neurodegenerative diseases. Microtubule depolymerizing agents such as colchicine or nocodazol were used in murine cerebellar granule cells (CGC) to mimic these pathological changes. Colchicine (1 µM) or nocodazol (1 µM) triggered fragmentation of microtubuli resulting in axo-dendritic degeneration followed by apoptosis. The microtubule stabilizing agent taxol prevented both fragmentation of microtubules and cell death. Apoptosis was accompanied by activation of caspases and phosphatidylserine (PS) translocation to the outer surface of the plasma membrane. Caspase inhibitiors prevented the initial apoptotic changes, although the axo-dendritic net was lost. Depletion of intracellular ATP by the mitochondrial poisons NO and MPP+ or by deoxyglucose prevented activation of caspases, exposure of the phagocytosis marker PS and apoptotic death, while the primary effect of microtubule disruption still occured. Conversely, repletion of cellular ATP by enhanced glycolysis restored all apoptotic features. These findings indicate that the intracellular ATP level may determine whether degenerating neurons are rapidly removed by apoptosis or whether they persist as severely damaged cells.

 

FUNCTIONAL STUDIES ON  p73

V. De Laurenzi, D. Barcaroli, A. Costanzo*, M. Ranalli, M. Levrero* and G. Melino

IDI-IRCCS, Biochemistry Lab, c/o Department of Experimental Medicine, University of Rome Tor Vergata; 00133 Rome, Italy. *Gene Expression Laboratory, Fondazione A. Cesalpino, University La Sapienza, 00161 Rome, Italy

 

The p53-homologue p73, has been mapped to a region (1p36.33) which is frequently deleted in neuroblastomas, suggesting that its alterations may play a role in the development of tumours of the nervous system. However, unlike p53, mutant p73 has rarely been found in human tumours. Few studies have directly investigated functions of p73, and their activities have been largely assumed based on their structural similarities with the p53 homologue.  Here we show that:

(1) p73 is expressed in human cells as several alternatively spliced forms, a, b, g, d, e and z which show different abilities to homo/hetero-dimerize with each other and with p53. (2) Induction of apoptosis by p73 in response to cisplatin is regulated by c-Abl. DNA damaging agents, through MLH1 and c-Abl, stabilize the protein level of p73 by increasing its half-life. (3) p73 functions as trigger of differentiation in neuroblastoma cell lines. Indeed, p73 expression is upregulated during neuroblastoma cell differentiation induced by dimethylsulphoxide and retinoic acid. Our results indicate that the overexpression of all p73 isoforms is sufficient to trigger the neuronal differentiation of neuroblastoma cells in vitro, while the transcriptionally inactive Ala156Val mutants (or dominat negative p73D84) of all isoforms failed to do so. p73-induced differentiation was accompanied by MYCN down regulation, NCAM transactivation, pRB down regulation. The ability of p73 to act as a determinant of neuronal differentiation is specific and it is not shared by their homologue p53, which is indeed capable to induce cell death under the same conditions. In conclusion, p73 seems involved both in tumour suppression and development.

 

Session IV: Neurology                                             Sunday April 2nd

 

Cleavage of Alzheimer's b-amyloid precursor protein by g-secretase liberates an intracellular peptide that promotes apoptosis

Brent Passer, Luca Pellegrini & Luciano D'Adamio

T-cell apoptosis Unit, Laboratory of Cellular and Molecular Immunology, NIAID, National Institutes of Health, Bethesda, Maryland 20892

 

It is believed that Alzheimer's Disease (AD) is a result of extracellular accumulation of the amyloidogenic form of Ab peptide (Ab42). Ab is produced by the sequential proteolysis of the b-amyloid precursor protein (APP) by b- and g- secretases1. Some Alzheimer's cases are familial (FAD) and are due to mutations in APP itself, presenilin-1 (PS1) or presenilin-2 (PS2) (ref. 2-5). Presenilins are highly homologous proteins that are required for g-secretase activity6. Of more importance, mutations in presenilins and APP are theorized to cause FAD by augmenting the formation of Ab42 (ref. 7,8). Aside from its pathological relevance, the physiological consequences of APP proteolysis remains unknown. The discovery that the three FAD genes enhance programmed cell death (PCD) has hinted at a potential link between the dysregulation of apoptosis and neurodegeneration observed in AD9-11. The parallelism between apoptotic and amyloidogenic effects suggests that the FAD proteins could modulate apoptosis by directing APP cleavage. Here we report that the APP intracellular domain (AID) fragment liberated after g-secretase cleavage acts as a positive regulator of apoptosis. Thus, overproduction of AID, as in the case of FAD, could add to the toxic effect of Ab42 aggregates in Alzheimer's patients further accelerating neurodegeneration.


 

Session V: TRAIL Signaling                    Monday April 3rd

 

TRAIL-induced apoptosis is not inhibited by overexpression of Bcl-2 or Bcl-xL

Henning Walczak, Axel Bouchon, Eva Rieser, Heiko Stahl, and Peter H. Krammer

Department of Immunogenetics, German Cancer Research Center, Im Neuenheimer Feld 280, 69120 Heidelberg, Germany

 

Tumor necrosis factor (TNF)-related apoptosis-inducing ligand (TRAIL) is a novel member of the TNF family and has recently been shown to exert tumoricidal activity in vivo in the absence of any observable toxicity. However, the signaling pathways triggered by TRAIL stimulation and the mechanisms involved in resistance against TRAIL-mediated apoptosis are still poorly defined. Therefore, we addressed the question to which extent the mitochondrial pro-apoptotic potential contributes to TRAIL-induced apoptosis and whether protection of mitochondria interferes with apoptosis mediated by TRAIL. We show that TRAIL-induced apoptosis involves late dissipation of mitochondrial membrane potential (ΔΨm) and cytochrome c release that follows activation of caspase-8 and caspase-3 and induction of DNA fragmentation. In addition, inhibition of caspase-8 but not caspase-9 or ñ3 prevents mitochondrial permeability transition (PT) and apoptosis. Various cell lines overexpressing the anti-apoptotic proteins Bcl-2 or Bcl-xL are not or only marginally protected against TRAIL-induced apoptosis. In contrast, apoptosis induced by the chemotherapeutic drug etoposide was severely impaired in these cells. Thus, TRAIL induces apoptosis via a caspase signaling cascade that executes apoptosis independently of the pro-apoptotic machinery of mitochondria. Since most chemotherapeutic drugs used in the treatment of malignancies lead to apoptosis by engagement of the mitochondrial pro-apoptotic machinery our data suggest a novel alternative anti-tumor strategy by using TRAIL against Bcl-2- or Bcl-xL-overexpressing tumors that have acquired resistance to conventional anti-tumor chemotherapy.

 

Structure of the apoptosis inducing TRAIL‑DR5 complex

Juthathip Mongkolsapaya1, Jonathan M. Grimes2, Nan Chen1, Xiao‑Ning Xu1, David I Stuart2, E. Yvonne Jones2 and Gavin R Screaton1

1M3C Human Immunology Unit, Institute of Molecular Medicine, John Radcliffe Hospital. Oxford OX3 9DS, UK; 2 Structural Biology, Wellcome trust Centre for Human Genetics, Roosevelt Drive, Headington, Oxford, OX3 7BN, UK

 

Apoptosis plays a significant role in the immune system in processes such as T cell development, cytotoxicity and T cell homeostasis. It can be initiated by the interaction of cell surface receptors with their cognate ligands. A paradigm for this interaction is TNF and TNF‑R1. These two proteins define two large families of type II and type I membrane proteins respectively. DR4 and DR5, which are the members of the TNF‑R family, both interact with the ligand TRAIL. TRAIL also interacts with two other receptors, DcR1, and DcR2, which have no or a truncated death domain and act as decoys preventing apoptotic signaling through DR4 and DR5. We have solved the crystal structure of a complex between TRAIL and DR5 at 2.2 A. Three receptor molecules are arranged around a central TRAIL trimer. An additional 15 amino acid loop and variability in the D and E strands of the TRAIL together with a change in the alignment of the two receptor domains are among a number of unique surface features which confer specificity of TRAIL for its receptors. 

 

Session V: Trail Signaling               Monday April 3rd

 

Caspase-8 and FADD/Mort1 are necessary components of the TRAIL-R2 Death-Inducing Signalling Complex (DISC)

Martin R. Sprick1, Markus A. Weigand1, Anne Grosse-Wilde1, Melanie Logemann1, Heiko Stahl1, Eva Rieser1, Peter Juo2, John Blenis2, Peter H. Krammer1, and Henning Walczak1

1Tumorimmunology Program, German Cancer Research Center, Heidelberg, Germany

2Department of Cell Biology, Harvard Medical School, Boston, Massachusetts, USA

 

The TNF-related apoptosis-inducing ligand (TRAIL) has been shown to induce apoptosis in a number of tumor cell lines while being non-toxic to normal tissues. Currently, five receptors have been shown to bind TRAIL, namely TRAIL-Receptor†(TRAIL-R)†1 to TRAIL-R4 and osteoprotegerin. Two of these receptors, TRAIL-R1 and TRAIL-R2, have been shown to induce apoptosis in a caspase-dependent manner. Recently, a number of studies have addressed the composition of the death-inducing signalling complex (DISC) associated with TRAIL-R1 and TRAIL-R2 by overexpressing at least one putative component of the TRAIL-DISC. Yet, it remained unclear which molecules are recruited to the DISC upon TRAIL stimulation under native conditions. We thus compared the protein complex induced by stimulation with TRAIL and CD95L under non-overexpression conditions in various cell lines. We could demonstrate that both FADD and Caspase-8 are necessary for the formation of the TRAIL-R2-DISC.

 

Active effector caspases and cleaved cytokeratins are sequestered into cytoplasmic inclusion following TRAIL-induced apoptosis

Marion MacFarlane, Wendy Merrison, David Dinsdale and Gerald M. Cohen

MRC Toxicology Unit, Hodgkin Building, University of Leicester, P.O. box 138, Lancaster Road, Leicester LEI 9HN, UK

 

Tumor necrosis factor-related apoptosis-inducing ligand (TRAIL)-induced apoptosis, in transformed human breast epithelial MCF-7 cells, resulted in a time-dependent activation of the initiator caspases-8 and -9 and the effector caspase-7. Cleavage of caspase-8 and its preferred substrate, Bid, preceded processing of caspases-7 and -9, indicating that caspase-8 is the apical initiator caspase in TRAIL-induced apoptosis. Using transient transfection of C-terminal tagged green fluorescent protein fusion constructs, caspases-3, -7 and -8 were localized throughout the cytoplasm of MCF-7 cells. TRAIL-induced apoptosis resulted in activation of caspases-3 and –7 and the redistribution of most of their detectable catalytically active small subunits into large spheroidal cytoplasmic inclusions, which lacked a limiting membrane. These inclusions, which were also induced in untransfected cells, conteined cytokeratins 8, 18 and 19, together with both a phosphorylated form and a caspase-cleavage fragment(s) of cytokeratin 18. Similar inclusions were found follwing TRAIL treatment of lung, cervical and non-transformed breast epithelial cells. We propose that effector caspase-mediated cleavage of cytokeratins, resulting in disassembly of the cytoskeleton and formation of cytoplasmic inclusions, may be a characteristic feature of epithelial cell apoptosis and that sequestration of active caspases within these inclusions may limit their potential damage to neighbouring cells.

 

Session VI: Trail biology                                  Monday April 3rd

 

Differential Regulation of the CD95- and TRAIL-System on Human Peripheral T†Lymphocytes

Markus A. Weigand, Martin Sprick, Anne Grosse-Wilde, Silke Maier, Dorothee Suess, Eva Rieser, Peter H. Krammer, and Henning Walczak

Department of Immunogenetics, German Cancer Research Center, Im Neuenheimer Feld 280, 69120 Heidelberg, Germany

 

Peripheral deletion of T cells is essential for the homeostasis of the immune system. This mechanism involves the CD95 and TNF system. Recently, also the TRAIL system has been postulated to contribute to peripheral deletion of T cells. However, the regulation and function of TRAIL and its receptors on peripheral T cells and intracellular apoptotic signaling pathways are largely unknown. Using monoclonal antibodies specific for the individual TRAIL-receptors we demonstrate that on freshly isolated human T†cells TRAIL-R1 and TRAIL-R2 are significantly expressed, while there is only marginal expression of TRAIL-R3 and TRAIL-R4. Whereas the CD95 receptor is upregulated upon stimulation of T cells with PHA/IL-2, TRAIL-receptor surface expression is not increased. Increased CD95 receptor expression is associated with increased sensitivity to CD95-mediated apoptosis. In contrast, peripheral T†cells are insensitive to TRAIL-induced apoptosis. This phenotype does not change during culture with various physiological stimuli. T cells can, however, be sensitized for TRAIL with cycloheximide or actinomycin D. Apoptosis induction by plate bound agonistic antibodies revealed that TRAIL-induced apoptosis in sensitized T†cells is mainly mediated by TRAIL-R2, while there is no significant role of TRAIL-R3 and TRAIL-R4 in determining the resistance of peripheral T†cells to TRAIL. TRAIL-induced apoptosis in T†cells is characterized by cleavage of caspase-8, caspase-3, PARP and DNA†fragmentation. These results suggest differential roles for the CD95 and TRAIL systems in the homeostasis of the immune system.

 

        INVOLVEMENT OF TRAIL RECEPTOR 2 IN THYMIC NEGATIVE SELECTION

A Katharina Simon & Gavin R Screaton

Institute of Molecular Medecine, Oxford, England

 

Developing T lymphocytes bearing self reactive antigen-receptors undergo apoptosis. This process called negative selection requires T cell mediated recognition of antigenic peptides+MHC as well as caspases. It is not known whether surface molecules other than the TCR such as death receptors are involved in negative selection. We have investigated the role of Trail and and its receptors 1 and 2 in the human thymus where negative selection can be mimicked by anti-CD3 or superantigens. Thymocytes are not susceptible to an anti-Trail receptor 2 (Trail-r-2) polyclonal antibody inducing death in the T cell line Jurkat. However, in the presence of a sublethal dose of anti-CD3 thymocytes die in response to the anti-Trail-r-2 antibody as well as in response to crosslinked soluble Trail. Furthermore in human thymus organ cultures lethal doses of anti-CD3 treatment can be inhibited by soluble Trail. Finally the depletion of superantigen-specific V beta families in thymus organ culture is inhibited by a soluble Trail-r-2 but not by soluble Fas or TNFr. These results indicate that Trail and Trail-r-2 play a role in anti-CD3 and superantigen induced deletion of thymocytes. It remains to be shown whether this is true in antigen-induced deletion and whether other death receptors play a role in negative selection.

 

Session VI: Trail biology                                  Monday April 3rd

 

Regulation of TRAIL sensitivity in primary and transformed human keratinocytes

M. Leverkus1, M. Neumann2, T. Mengling1, E.- B. Bröcker1, P. H. Krammer3 and H.Walczak3

Department of 1Dermatology and 2Pathology, University of Würzburg, Germany, 3Tumor Immunology Program,German Cancer Research Center, Heidelberg, Germany

 

Tumor necrosis factor (TNF)-related apoptosis-inducing ligand (TRAIL) has been shown to exert potent cytotoxic activity against many tumor cell lines but not against normal cells. It has been hypothesized that this difference in TRAIL sensitivity between normal and transformed cells might be due to the expression of the non death-inducing TRAIL receptors (TRAIL-R) TRAIL-R3 and TRAIL-R4, presumably by competition for limited amounts of TRAIL. In order to assess the regulation of resistance versus sensitivity to TRAIL in primary as well as transformed keratinocytes, we examined TRAIL sensitivity, TRAIL receptor expression and intracellular signalling events induced by TRAIL. Although TRAIL induced apoptosis in primary as well as transformed keratinocytes, a marked difference in sensitivity could be observed with primary keratinocytes (PK) being five-fold less sensitive to TRAIL than transformed keratinocytes (TK). Yet, both cell types exhibited similar TRAIL receptor surface expression, suggesting that expression of TRAIL-R3 and TRAIL-R4 may not be the main regulator of sensitivity to TRAIL. Biochemical analysis of the signalling events induced by TRAIL revealed that PK could be sensitized for TRAIL and, similarly, for TRAIL-R1-, and TRAIL-R2-specific apoptosis by pretreatment of the cells with cycloheximide (CHX). This sensitization concomitantly resulted in processing of caspase-8, which did not occur in TRAIL-resistant PK. These data indicate that an early block of TRAIL-induced apoptosis was present in PK as compared to TK or PK treated with CHX. Interestingly, cFLIP levels, high in PK and low in TK and several other squamous cell carcinoma cell lines, decreased rapidly after treatment of PK with CHX correlating with the increase in TRAIL sensitivity and caspase-8 processing. Furthermore, ectopic expression of cFLIPL in TK by transfection with a cFLIPL expression vector resulted in resistance to TRAIL-mediated apoptosis of these cells. Thus, our results demonstrate that TRAIL sensitivity in PK is primarily regulated at the intracellular level rather than at the receptor level.

 

Session VII: Clinical aspects of apoptosis                  Monday April 3rd

 

FLIP (FLAME-1/I-FLICE) and Bcl-xL protect thyrocytes from Fas-mediated destruction in Graves’ disease

Giorgio Stassi1, Diana Di Liberto1, Ann Zeuner2, Matilde Todaro1, Felicia Farina1,  Antonella Stoppacciaro3,  Luigi Ruco3, Francesco Grignani4 and Ruggero De Maria2.

1Istituto di Anatomia Umana, University of Palermo; 2Istituto di Patologia Generale, University of Catania; 3Dipartimento di Medicina Sperimentale e Patologia, University of “La Sapienza”, Roma; 4Istituto di Clinica Medica, University of Perugia

 

We previously demonstrated that following autoimmune inflammation, autocrine or paracrine interactions between Fas and its ligand (FasL) mediate thyrocyte destruction in Hashimoto’s thyroiditis (HT). Differently from HT, thyroid autoimmune processes leading to Graves’ disease (GD) result in autoantibody-mediated TSH receptor stimulation rather than in thyrocyte destruction. Given that thyrocytes constitutively express FasL, we have investigated why autoimmune inflammation in GD does not seem to proceed to Fas-mediated thyrocyte destruction. Immunohistochemical and immunoblot analyses of thyroid samples showed that all GD thyrocytes constitutively express FasL, while Fas was mostly detected in thyrocytes in proximity to infiltrating lymphocytes. However, differently from HT, we could not detect neither apoptosis nor caspase activation in vivo in Fas-positive GD thyrocytes. Importantly, extensive searching for pro-apoptotic and anti-apoptotic factors in thyrocytes showed that HT thyrocytes overexpressed caspase-8 and caspase-3, the dominant mediators of Fas-induced apoptotic cascade. By contrast, GD thyrocytes overexpressed FLIP and Bcl-xL, two major anti-apoptotic proteins. Importantly, analysis of freshly isolated primary thyrocytes transduced with either FLIP or Bcl-xL showed that both proteins were able to completely block FasL-induced apoptosis in thyrocytes, suggesting a major role for FLIP or Bcl-xL in protection from thyrocyte depletion in GD. Taken together, our results provide molecular evidence explaining the presence or the absence of thyrocyte destruction in thyroid autoimmune diseases.

 

Apoptotic pathway in cardiomyocytes

G. Condorelli, M.Latronico, R. Roncarati, J.K. Aycock, F. Farina, John Ross, Jr., G. Stassi

II Faculty of medicine, “La Sapienza” University, Rome; Kimmel Cancer Center, Thomas Jefferson University; UCSD, La Jolla, CA; Human Anatomy Section, University of Palermo

 

Heart failure (HF) is a final pathological condition in cardiovascular diseases of various etiology. Cardiomyocyte cell loss characterizes HF and accounts for the decreased cardiac function. We have investigated whether cardiomyocyte apoptosis plays a causal role in HF. As model systems, we used isolated neonatal cardiomyocytes, transgenic animals, a rat model of pressure-overload HF and human specimens from HF patients. We determined the contribution of the pro- and anti-apoptotic pathways generated from the TNF-a receptors in cardiomyocyte survival. Moreover, we are determining the relative contribution of pathways generated from gp130 in rescuing cardiomyocytes from oxidative stress. We have also associated cardiomyocyte apoptosis with decompensation of cardiac function during pressure overload. To determine whether apoptotic genes play a causal role in HF, transgenic mice expressing selectively in the cardiomyocyte compartment apoptotic genes were generated. Pro-caspase 3 overexpression induced a mild phenotype in unstressed animals; on the contrary, mice were prone to death after ischemia-reperfusion injury. Bcl-xl overexpression rescues the HF phenotype of genetically induced HF. All together, our data strongly suggest that by modulating the activity of apoptotic genes, it is possible to alter the course of HF.

 

Session VII: Clinical aspects of apoptosis                  Monday April 3rd

 

Cyclosporin A-insensitive CD95 (Fas) ligand expression in the pathogenesis of acute intestinal Graft-versus-Host Disease

Christoph Wasem*, Corina Frutschi*, Diana Arnold*, Tesu Liná, Douglas R. Greenß, Christoph Mueller*, and Thomas Brunner*

*Division of Immunopathology, Institute of Pathology, University of Berne, Switzerland, áGI Division, Department of Medicine, Northwestern Medical School, Chicago, IL, USA, and ßLa Jolla Institute for Allergy and Immunology, San Diego, CA, USA

 

Graft-versus-host disease (GvHD) represents a serious complication after bone marrow transplantation. Anti-host immune responses are often treated with the immunosuppressant cyclosporin A (CsA), however, with limited success. We have previously shown in an experimental model for acute intestinal GvHD that expression of CD95 (Fas/APO-1) ligand by donor-derived T cells and resulting cytotoxicity is a crucial disease-promoting factor. We have thus investigated whether CsA can block activation-induced CD95 ligand expression by donor-derived T cells and whether CD95 ligand expression is impaired during GvHD. Whereas CsA was found to efficiently inhibit activation-induced CD95 ligand expression in control splenic and intestinal intraepithelial lymphocytes, it only marginally affected CD95 ligand expression by activated donor-derived T cells during GvHD. This was found to be the result of extensive in vivo accumulation and storage of intracellular CD95 ligand protein which is released in a protein synthesis-independent and CsA-insensitive manner. In addition, in vivo treatment of animals with CsA completely blocked T cell responses to tetanus toxoid but could only partially reverse the development of GvHD and CsA-insensitive CD95 ligand expression, suggesting that alternative, calcineurin-independent, signaling pathways may be involved in CD95 ligand expression and cytotoxicity during GvHD.

 

Proapoptotic FasL Is present in Normal Kidney Tubules and Inflammed Glomeruli

C. Lorz, A. Ortiz, P. Justo, J. Egido.

Fundacion Jimenez Diaz, Universidad Autonoma de Madrid, Madrid, Spain

 

Fas expression is increased during renal injury and Fas activation promotes glomerular injury. However, there is little information on FasL expression in the kidney. We now report that FasL is present in normal mouse and rat kidney. In situ hybridization and immunohistochemistry showed that renal tubular epithelium is the main site of Fasl expression in the normal kidney. De novo FasL expression by glomerular cells was present in two models of glomerular injury: rat immune‑complex proliferative glomerulonephritis and murine lupus nephritis. FasL was also detected in murine proximal tubular epithelial cells in culture. The biological significance of tubular epithelial cell FasL was further investigated. Tubular epithelium‑derived FasL Induced apoptosis in Fas sensitive lymphoid cell lines (A20) but not in Fas resistant lymphoid cell lines (A2OR). Neutralizing anti‑FasL antibodies prevented this effect. By contrast, non‑stimulated tubular epithelial cells well relatively resistant to apoptosis induced by high concentrations of FasL and FasL did not induce apoptosis in an autocrine fashion. However, tubular epithelial cells stimulated with inflammatory mediators that increased cell surface Fas expression were sensitized to apoptosis induced by FasL.

 

Session VII: Clinical aspects of apoptosis                  Monday April 3rd

 

Quantitative analysis of CD95 and CD95L mRNA expression in HIV infection

Marcello Pinti, Jessica Pedrazzi, Milena Nasi, and Andrea Cossarizza

Department of Biomedical Sciences, University of Modena and Reggio Emilia, Italy

 

We developed a quantitative-competitive RT-PCR assay for the analysis of the 2 main forms of CD95 mRNA and for CD95L mRNA, and studied their levels in chronic and acute HIV infection. A301 and its infected clone ACH-2 mounted the same amount of plasmamembrane CD95, but have different ratios between total and membrane form of CD95 mRNA. In comparison with U937 cells, the infected clone U1 had a consistent decrease in CD95 expression, mirrored by a decrease in membrane CD95 mRNA. In respect to A301, ACH-2 expressed about 400 (basal) or 10 (induced) fold less CD95L mRNA, which was undetectable in U937 and U1. Almost all lymphocytes from patients with primary HIV infection were CD95+; anti-CD95 mAbs or binding to CD95L+ cells induced rapid apoptosis, but CD95L mRNA was not expressed, and poorly inducible. Our data indicate that a complex balance exists between proapoptotic events, likely triggered by the host to limit viral production, and anti-apoptotic events likely triggered by the virus to increase its production and survival.

 

Session VIII: Transcriptional regulation of apoptosis   Tuesday April 4th

 

Steroid regulation of programmed cell death during Drosophila development.

Eric H. Baehrecke. 

Center for Agricultural Biotechnology, University of Maryland Biotechnology Institute, College Park, MD 20742

 

The steroid hormone ecdysone activates caspase-dependent cell death of salivary glands. Salivary gland cell death is preceded by increased transcription of rpr and hid, the CED4 homologue dark, the capase dronc, and several ecdysone-regulated transcription factors. The ecdysone-regulated EcR, BR-C and E74 genes regulate cell death, but their function in other processes indicate that more specific mediators of cell death exist. E93 is a steroid-regulated gene that is expressed in dying cells, and encodes a novel nuclear protein. BR-C, E74 and E93 function are required for programmed cell death of salivary glands, and E93 mutant salivary glands are arrested prior to changes in the cytosol and plasma membrane that accompany this cell death. Expression of E93 results in programmed cell death that reflects the pattern of ectopic expression. E93 requires the function of the H99 genetic interval that contains the rpr, hid, and grim cell death genes to induce nuclear changes diagnostic of apoptosis. In contrast, expression of E93 is sufficient to induce the removal of cells and engulfment by phagocytes in the absence of the H99 genes. These studies indicate that E93 regulates a novel cell death program involving the coordination of distinct caspase-mediated subcellular events, and specifies steroid-activated destruction of cells.

 

Natural retinoic acids inhibit the activation induced T-cell death by modifying the function of Nur77

Eva Szegezdi1, Uwe Reichert2, Laszlo Fesus1 and Zsuzsa Szondy1

1Medical School of Debrecen, Department of Biochemistry and Molecular Biology

2Centre International de Recherches Dermatologiques Galderma, Sophia Antipolis, France

 

Crosslinking of the T-cell receptor (TCR) induces cell death in T-cells that is based on Fas/FasL interaction. The TCR activation can initiate the translocation of FasL in the membrane or it can induce FasL expression. The activation of FasL requires the expression of the Nur77 orphan nuclear receptor family members, in case of the lack of this step no apoptosis happens. Natural retinoic acids inhibit TCR mediated cell death without inhibiting the expression of Nur77. The goal of our studies was to identify the step where retinoic acids interfere with the TCR signalling pathway. In our experiments the effect of various retinoic acid analogues on the activation-induced apoptosis of Jurkat T-cells was studied. It was proven that the TCR activation initiates de novo FasL synthesis, while natural retinoids prevented it. To determine which signalling pathway is modified by retinoids Jurkat cells were transfected with a vector carrying a Nur77 response element (NBRE) connected to luciferase reporter gene. Our results show that all trans retinoic acid and the RARa analogue prevented the increase of Nur77 transactivation initiated by T-cell receptor activation. The results show that retinoids act through the RARa receptor in the Nur77 signalling pathway. By decreasing the DNA binding activity of Nur77 they regulate activation induced cell death.

 

Session VIII: Transcriptional regulation of apoptosis   Tuesday April 4th

 

Apolipoprotein J (Clusterin), a protein required for neuroblastoma cell survival, is directly regulated by the B-myb oncoprotein and expressed in advanced disease stages

Maria Cervellera 1, Giuseppe Raschella 2, Giorgia Santilli 1, Barbara Tanno 2, Andrea Ventura 1, Camillo Mancini 2, Bruno Calabretta 3, and Arturo Sala 1*.

1Laboratory of Molecular Pharmacology and Pathology, Consorzio Mario Negri Sud, 66030 S. Maria Imbaro, Italy; 2ENEA Section of Toxicology and Biomedical Sciences, 00060 Rome, Italy; 3Department of Microbiology/Immunology, Kimmel Cancer Institute, Thomas Jefferson University, Philadelphia, PA 19107

 

B-Myb is a ubiquitiously expressed transcription factor involved in the regulation of cell survival, proliferation, and differentiation. B-myb expression in neuroblastoma correlates with advanced stages of the disease and poor patients1 survival. In an attempt to isolate B-Myb-regulated genes which may explain the role of B-Myb in tumorigenesis, RDA (Representational Difference Analysis) was performed in neuroblastoma cell lines with different levels of B-Myb expression. One of the genes whose mRNA levels were enhanced in B-Myb expressing cells was ApoJ/Clusterin SGP-2/TRMP-2 (ApoJ/Clusterin, thereof), previously implicated in cell survival. Here we show that the human ApoJ/Clusterin gene contains in its 51 flanking region a Myb-binding site which interacts with bacterially synthesized B-Myb protein and mediates B-Myb-dependent transactivation of the ApoJ/Clusterin promoter in transient transfection assays. Moreover, ApoJ/Clusterin expression was detected in most tumor samples of neuroblastoma patients in advanced disease stages. Neuroblastoma cell lines transfected with a ApoJ/Clusterin antisense expression vector showed reduced resistance to apoptosis induced by the chemiotherapic drug doxorubicin. These results suggest that aberrant B-Myb expression may promote tumor progression in neuroblastoma patients by induction of ApoJ/Clusterin expression and increased resistance to apoptotic cell death.

 

INTERFERON REGULATORY FACTOR-1 AND -2 regulate constitutive and INTERFERON-GAMMA-induced expression of multiple caspases in monocytic cells

Ann Zeuner1, Adriana Eramo3, Giovanni Rizzo2, Livia Manzella1, Angelo Messina1, Cesare Peschle3, Francesco Grignani2 and Ruggero De Maria2

Istituto di Patologia Generale, University of Catania1; Istituto di Clinica Medica, University of Perugia2; Laboratorio di Ematologia e Oncologia, ISS, Rome3

 

Caspases are central components of the apoptotic machinery, responsible for proteolytic cleavage of key substrates and regulated cell disassembly. Interferon-gamma (IFN-g) has been shown to increase sensitivity to apoptosis in a variety of cells, but the molecular mechanisms underlying this phenomenon have not been identified. We found that exposure of monocytic cell lines to IFN-g induces upregulation of several caspases, including caspase-1, caspase-2, caspase-3, caspase-7 and caspase-8 in, resulting in enhanced susceptibility to cell death following a variety of apoptotic stimuli. In order to identify IFN-g-induced transcriptional activators of caspases, the monocytic cell line U937 was transfected with interferon regulatory factor-2 (IRF-2), a negative regulator of interferon transcription. Unexpectedly, IRF-2 expression completely abolished both constitutive and IFN-g-induced expression of multiple caspases, suggesting that IRF-2 inhibits several pro-apoptotic genes by acting as dominant negative of interferon consensus sequence binding proteins. Importantly, U937 cells stably transfected with an antisense for interferon regulatory factor-1 (IRF-1) displayed the same phenotype of IRF-2 overexpressing cells, demonstrating that IRF-2 acts by targeting endogenous IRF-1, which is required for constitutive and IFN-g-induced expression of multiple caspases. These findings may explain the anti-oncogenic and oncogenic potentials of IRF-1 and IRF-2.

 

Session VIII: Transcriptional regulation of apoptosis    Tuesday April 4th

 

CASPASE-MEDIATED TAL-1 CLEAVAGE IS REQUIRED FOR ERYTHROID CELL APOPTOSIS

Adriana Eramo1,2, Ann Zeuner1,3, Nadia Felli1, Srinivasa M. Srinivasula2, Emad S. Alnemri2, Ugo Testa1, Gianluigi Condorelli2, Cesare Peschle1,2, Ruggero De Maria2,3.

Dept. of Hematology-Oncology Istituto Superiore di Sanita’, Rome, Italy1; Kimmel Cancer Institute, Thomas Jefferson University, Philadelphia, PA2; Institute of General Pathology, University of Catania, Italy3

 

We previously demonstrated that caspase-mediated cleavage of GATA-1 results in growth and differentiation arrest of immature erythroid cells, as a major mechanism responsible for negative regulation of erythropoiesis. TAL-1 is a helix-loop-helix trascription factor required for early blood cell development and terminal erythropoiesis. Immunofluorescence and immunoblot analysis showed that prolonged death receptor (DR) stimulation in erythroid cells induced TAL-1 and Bcl-xL downregulation prevented by caspase inhibitors. Direct demonstration that TAL-1 is a target of caspases was obtained by testing wild type and putative caspase-resistant TAL-1 mutants for in vitro and in vivo cleavage. Recombinant caspase-3, -7 and -8 were able to cleave TAL-1 in vitro at Asp 180 and Asp 293. A similar cleavage pattern followed by proteolytic TAL-1 degradation was found in vivo by analyzing CD95-stimulated erythroblasts and lymphoid cell lines expressing TAL-1. Importantly, expression of a caspase-resistant TAL-1 double mutant (D180E and D293E) in erythroid progenitors was able to prevent amplification of caspase activation, GATA-1 degradation, Bcl-xL downmodulation, and impaired erythropoiesis induced by erythropoietin deprivation or DR triggering. The antiapoptotic activity of uncleavable TAL-1 was particularly evident in the presence of low levels of erythropoietin and saturating amount of CD95L, a culture condition that did not allowed survival of erythroid cells expressing caspase-resistant GATA-1. Immunoblot and semiquantitative RT-PCR analysis in erythroid cells showed that TAL-1 induced a strong upregulation of Bcl-xL, the major erythroid antiapoptotic factor. In conclusion, we provide evidence that TAL-1 acts as a survival factor in erythroid cells by sustaining Bcl-xL expression and preventing massive caspase activation

 

Novel approach for enhancing the susceptibility of cancer cells to chemotherapeutic drug induced apoptosis: Inhibition of NF‑kB through intracellular delivery of IkB by HSV-1 structural protein VP22

Christopher Stroh, Juergen Held, Wolfgang Wybranietz, and Klaus Schulze-Osthoff

Institute of Experimental Dermatology, University of Muenster, Germany

 

One major problem in chemotherapy of cancer is the activation of the transcription factor NF‑kB by many of the used chemotherapeutic compounds thereby rendering the cells more resistant to apoptosis. A promising strategy for increasing the effectiveness of chemotherapeutic drugs is the inhibition of NF‑kB by overexpression of its inhibitory protein IkBa. However, an unsolved problem of these genetherapeutic approaches is the low transfection efficiency. Here we report the intracellular delivery of IkBa by VP22, a structural protein of herpes simplex virus type 1 (HSV‑1). VP22 has the unique feature that upon transfection the expressed protein migrates out of transfected cells and is taken up by virtually all surrounding cells where it accumulates in the nucleus. This intercellular transport was also shown to be possible with VP22 fusion proteins. To take advantage of the possibility to deliver IkBa to nearly 100% of target cells several VP22‑IkBa constructs were made and tested. The expressed VP22‑IkBa fusion proteins proved to be highly effective in inhibiting the activation of NF‑kB and enhancing the susceptibility to apoptosis of different cell cell lines after TNF and etoposide treatment. When cell‑free extracts of cells expressing either VP22, IkB, or VP22‑IkBa proteins were incubated with HeLa cells VP22 and VP22‑IkBa but not IkBa were taken up into the cells within min. Only VP22‑IkBa proteins were able to block NF‑kB activation in this import assay. At present we are performing large scale purification of VP22‑IkBa constructs to examine their effect in in vivo models.

 

Session IX: Anti- and pro-apoptotic mechanism               Tuesday April 4th

 

Follicular dendritic cells provide GC B cells with two anti-apoptotic signals

Marco van Eijk and Cornelis de Groot

Cell Biology and Histology, Academic Medical Center, University of Amsterdam, Meibergdreef 15, 1105 AZ, Amsterdam

 

Follicular dendritic cells (FDCs) select B lymphocytes that have undergone affinity maturation of their B cell receptors (BCR) during germinal center (GC) reactions. Recently, we demonstrated that GC B cells apoptosis requires cathepsin activity downstream of caspase-3. Moreover, we showed that FDCs keep the caspase route inactive and additionally switch off endonuclease. Interestingly, FDCs contain cytoplasmic cystatin A, a natural inhibitor of cathepsins. Therefore we investigated this protein and its anti-apoptotic properties towards GC B cells. We showed that cystatin A was present in and was secreted by FDCs. Moreover, we demonstrated that recombinant cystatin A could block endonuclease activity of GC B cells and that anti-cystatin A antibodies reverted endonuclease inhibition. Furthermore, we showed that the cystatin A protein is found back in the GC B cells after contact with the FDCs. Finally, we demonstrated that B cells present in FDC-B cells clusters upregulate FLIP. From these data we conclude that FDCs provide binding GC B cells with two anti-apoptotic signals: cystatin A blocks endonuclease activity in GC B cell nuclei and FLIP expression blocks Fas signalling.

 

Engagement of CD4 before TCR triggering regulates both Bax- and Fas-mediated apoptosis

L. Tuosto*, F. Somma*, M.M. Di Somma*, M.S. Gilardini Montani°, E. Cundari§ and E. Piccolella*.

*Dept. Cell. and Develop. Biol. University of Rome "La Sapienza", Italy; °Dept. Environmental Sciences, University "Della Tuscia", Viterbo, Italy; §Center of Evolutionary Genetics, CNR, Rome, Italy

 

In this work we wanted to clarify the CD4-dependent molecular mechanisms which regulate the susceptibility to both Fas- and bcl-2-dependent apoptotic pathway of antigen-activated human memory T cells.To address this issue, we used an experimental system of viral and alloantigen-specific T cell lines and clones and two ligands of CD4 molecules, Leu3a mAb and HIV gp120. We demonstrate that CD4 engagement before TCR triggering suppresses the TCR-mediated transcription of Flice-inhibitory protein (FLIP) and transforms memory T cells from an AICD-resistant phenotype to an AICD-susceptible phenotype. Moreover, the evidence that FasL mRNA expression was inhibited but the apoptotic programs were executed prompted us to analyze bcl-2 dependent pathways. The data demonstrate that while Bax and Bcl-2 expressions are coordinately modulated by antigen-activation, the engagement of CD4 separately from TCR influences the expression of the proapoptotic protein Bax independently of the anti-apoptotic protein Bcl-2. The increased expression of Bax was associated to the dissipation of the mitochondrial transmembrane potential (DYm) suggesting a novel immunoregulatory function of CD4 and demonstrating that both PCD and AICD are operative in CD4+ memory T cells. Furthermore, the analysis of the mechanisms by which IL-2 and IL-4 cytokines exert their protective function on anti-CD4 treated T cells show that they were able to revert the susceptibility to Bax-mediated but not to Fas-dependent apoptotic pathways.

 

Session IX: Anti- and pro-apoptotic mechanism              Tuesday April 4th

 

REQUIREMENT FOR TRANSFORMING GROWTH FACTOR-beta-1 (TGF-b1) IN CONTROLLING T CELL APOPTOSIS

Wanjun Chen, Wenwen Jin, Hongsheng Tian and Sharon M. Wahl

Cellular Immunology Section, OIIB, NIDCR, NIH, USA

 

TGF-b1, a potent immunoregulatory molecule, was found to control the life and death decisions of T lymphocytes. Both thymic and peripheral T cell apoptosis was increased in mice lacking TGF-b1 compared to wildtype littermates. Engagement of the T cell receptor enhanced this aberrant T cell apoptosis as did signaling through either the death receptor Fas or the TNFa receptor. Strikingly, the absence of TGF-b1 resulted in disruption of mitochondrial membrane potential (Dm) in these T cells, which marks the point of no-return in a cell condemned to die. Thus, TGF-b1 may protect T cells at multiple sites in the death pathway, particularly by maintaining the integrity of mitochondria. These findings may have broad implications not only for T cell selection and death in immune responses and in the generation of tolerance, but also for defining the mechanisms of programmed cell death in general

 

Map kinase‑mediated regulation of Fas, TNF and TRAIL receptor‑induced apoptosis in HeLa cells

Stefanie Tran, Tim Holmstrom and John Eriksson

Turku Centre for Biotechnology, P.O.Box 123, FIN‑20500 Turku, Finland

 

TNF, Fas, and TRAIL receptors are highly specific physiological mediators of apoptosis. Previously we have shown that some FasR‑insensitive cell lines are able to redirect the signal from apoptosis into survival by induction of MAPK/ERK. HeLa cells are insensitive both to FasR and TNF‑R1 and TRAIL‑Rs‑induced apoptosis. Therefore we wanted to determine whether MAPK could have a similar effect on other death receptor signaling. Inhibition of MAPK was sufficient to sensitize the cells to FasR and TRAIL‑Rs‑mediated apoptosis but not to signaling by TNF‑R1 which can be explained by the fact that TNF‑R1 but not FasR nor TRAIL‑Rs stimulation could strongly activate NF‑kB, a known survival mechanism. However, when the cells were sensitized with cycloheximide, overexpression of constitutively active MKK1 could rescue the cells from apoptosis induced by all three respective receptors, indicating that MAPK has a dominant protecting effect over death receptor stimulation. The protection occurs at the level or upstream of caspase‑8 and is protein synthesis independent. Current studies aim at characterizing the molecular mechanisms behind this effect.

 

Session IX: Anti- and pro-apoptotic mechanism              Tuesday April 4th

 

Charachterization of TGase-2 KO mice

Bernassola F., Corazzari M., Barcaroli D., Melino G. and De Laurenzi V

Dept. of Experimental Medicine, University of Rome Tor Vergata, Via di Tor Vergata 135, 00133 Rome, Italy

 

Tissue-Transglutaminase (tTG or TGase 2) is a Ca++-dependent enzyme that catalyses either e-(g-glutamyl)lysine or N1, N8 (g-glutamyl) spermidine isopeptide bonds. At least in some models, TGase 2 expression has been associated with apoptosis and it has been proposed that its activation leads to the irreversible assembly of a cross-linked protein scaffold in cells undergoing apoptosis. This results in a strong structure which is resistant to mechanical and chemical attacks. Thus, TGase 2-catalyzed protein polymerisation contributes to the ultrastructural changes typical of dying apoptotic cells; in addition, it stabilise the integrity of the apoptotic cells preventing the release of harmful intracellular components into the extracellular space and, consequently, inflammation and scar formation. The construct used for the targeting deleted part of exon 5, exon 6 containing the active site and intron 5. One in 1,500 clones was found recombined, allowing the production of hetero/homo-zygous mice. Complete absence of TGase 2 was demonstrated RT-PCR and western blot analysis. Transglutaminase activity measured on liver and thymus extracts showed however a minimal residual activity in TGase 2 -/- mouse. PCR analysis of RNA extracted from the same tissues demonstrated that at least TGase 1 (normally present in the skin) is also expressed in this tissues and could be responsible for the residual minimal activity. TGase 2 -/- mice showed no major developmental abnormalities, and histological examination of the major organs appeared normal. Induction of apoptosis ex vivo in TGase 2 -/- thymocites and in vitro on TGase 2 -/- Mouse Embryonal Fibroblasts showed only minor differences.

 

FLIP activates NF-kB and ERK signaling pathways and can divert Fas ligand-induced death signals to survival

Nils Holler#, Takao Kataoka#, Ralph C. Budd*#, Fabio Martinon#, Kim Burns#, Michael Hahne#, Margot Thome#, Norman Kennedy* and Jürg Tschopp#

#Institute of Biochemistry, University of Lausanne, BIL Biomedical Research Center, Chemin des Boveresses 155, CH-1066 Epalinges, Switzerland

*Immunobiology Program, Department of Medicine, The University of Vermont

 

Activation of Fas (CD95) by its ligand (FasL) rapidly induces cell death through recruitment and activation of caspase-8 via the adaptor protein FADD. However, Fas signals do not always result in apoptosis, but can also trigger a pathway that leads to proliferation. We investigated at what level the two conflicting Fas signals bifurcate and what protein(s) might be inplicated in switching the response. We found that under conditions where proliferation of CD3-activated human T lymphocytes is increased by recombinant FasL, there is recruitment of the caspase-8 inhibitor and FADD-interacting protein FLIP occurs. Fas-recruited FLIP can interact with TRAF1, TRAF2 as well as with the kinases RIP and Raf-1, resulting in the activation of the NF-kB and ERK signaling pathways. In T cells these two signal pathways are critical for IL-2 production and indeed, increased expression of FLIP in T cells results in enhanced IL-2 production. We provide evidence that FLIP is not simply an inhibitor of death-receptor induced apoptosis but that FLIP also mediates the activation of NF-kB and ERK signaling pathways by virtue of its capacity to recruit the respective adaptor proteins. Thus, FLIP can switch the pro-apoptotic activity of Fas to differentiation and/or proliferation

 

Session IX: Anti- and pro-apoptotic mechanism               Tuesday April 4th

 

The pro- and anti- apoptotic properties of cFLIPshort depend upon its intracellular compartmentalisation

Frank Neumann and Gerard Evan*

Imperial Cancer Research Fund, 44 Lincoln’s Inn Fields, London WC2A 3PX, UK. *Present address: UCSF Cancer Center, 2340 Sutter Street, Room S-233, San Francisco, California 94143-0218,USA

 

The death effector domain containing E8 gene product from equine herpesvirus-2, designated FLICE inhibitory protein (vFLIP), and its cellular homologue, cFLIPshort, have been reported to inhibit the activation of caspase-8 by death receptors. The cFLIPshort in contrast to its viral counterpart has also been described to act as a potent inducer of apoptosis. We report here that the pro-apoptotic effect of cFLIPshort when expressed above a certain threshold is mediated through intracellular filaments similar to the recently described death effector filaments (DEF). The vFLIP is incapable of forming DEF-like structures and acts thereby independent of its expression level exclusively as an anti-apoptotic protein. The cFLIPshort protein, however, only exhibits its protective site against CD95 induced death when present in a disperse cellular localisation. The coexpression of the vFLIP E8 protein interferes with DEF formation thus allowing the accumulation of cFLIPshort as a protective protein. The expression of members of the Bcl-2 family also prevents cFLIPshort to form DEF-like structures. Endogenous DEF-like structures by cFLIP can be detected after treatment with the anti-tumor ether lipid ET-18-0CH3 that is thought to act intracellulary upon the CD95 receptor. We conclude that the pro- or anti-apoptotic property of cFLIPshort depends upon its intracellular compartmentalisation.

 

Session X: Heat Shock Proteins                  Tuesday April 4th

 

Hsp70 protects tumour cells from cell death by at least two distinct mechanisms  

Marja Jäättelä and Jesper Nylandsted.  

Apoptosis Laboratory, Danish Cancer Society, Strandboulevarden 49, DK-2100 Copenhagen, Denmark

 

The major heat shock protein Hsp70 protects cells from cell death induced by tumour necrosis factor, heat and several chemotherapeutic drugs. Hsp70 is a chaperone protein containing an ATP binding domain capable of hydrolysing ATP and a peptide binding domain binding to the substrates. To study its mechanism of action, we expressed the wild type Hsp70 or its deletion mutants lacking these domains in apoptosis sensitive WEHI-S tumour cells. Whereas wild type Hsp70 conferred an effective protection against apoptosis induced by heat and TNF, the deletion mutant lacking the ATP binding domain protected only against heat and the deletion mutant lacking the peptide binding domain protected only against TNF. The protection from heat occurred prior to the activation of caspases, whereas protection from TNF took place downstream of the activation of caspase-3-like proteases. Thus, Hsp70 can inhibit apoptosis at two different steps of the apoptotic pathway by two clearly distinct mechanisms utilising different domains of the protein.

 

Interaction of SODD with Hsp70/Hsc70 via the BAG domain

Martinon Fabio, Jean-Luc Bodmer and Jürg Tschopp

Institute of Biochemistry, University of Lausanne, Chemin des Boveresses 155, CH-1066 Epalinges, Switzerland

 

Spontaneous signalling events through death domain (DD) containing receptors have to be prevented as they can result in inappropriate cell death. A novel protein has been charachterized (SODD, for silencer of DD) that binds to the DD of non activated TNF-receptor 1 thereby negatively regulating its signaling capacities. We identified an Hsp70/Hsc70 binding domain in SODD: the BAG domain. We found that the BAG domain of SODD interacts with the ATPase domain of Hsp70/Hsc70. Hsp70 interacts with the death receptor TRAMP/DR3 in the presence of SODD. We propose that SODD may act as an adaptor protein that targets Hsp70/Hsc70 to the cytoplasmic domain of death receptors, thereby locking them in a silent state.

 

Session X: Heat Shock Proteins                   Tuesday April 4th

 

Inhibition of Hsp70 synthesis leads to apoptotic death of breast cancer cells

Jesper Nylandsted, Karsten Brand, Michael Strauss and Marja Jäättelä.

Apoptosis Laboratory and Department of Cell Cycle and Cancer, Danish Cancer Society, Copenhagen, Denmark and Max-Planck- Gesellschaft, Max Delbrück Centre for Molecular Medicine, Berlin-Buch, Germany

 

Hsp70 is an anti-apoptotic chaperone protein preferentially expressed in human tumors and tumor cell lines. Here, we demonstrate that the expression of Hsp70 is required for the survival and growth of human breast cancer cells. Inhibition of the synthesis of Hsp70 by adenoviral transfer of antisense Hsp70 cDNA (Ad.asHsp70) resulted in massive apoptosis of all breast cancer cell lines tested, whereas the survival of non-transformed breast-derived cells were not affected. Anti-apoptotic proteins Bcl-2 and Bcl-x as well as caspase-inhibitors CrmA, ZVAD-FMK and DEVD-CHO failed to rescue tumor cells from Ad.asHsp70-induced apoptosis. Furthermore, sensitivity of breast cancer cells to Ad.asHsp70-induced apoptosis was independent of the expression of functional p53 tumor suppressor protein and estrogen receptor. Thus, the inhibition of the synthesis or the function of Hsp70 may form basis for the development of novel highly specific strategies for treatment of otherwise therapy resistant breast tumors.

 

Session XI: Apoptosis and tumors                      Tuesday April 4th

 

Immune escape of tumors in vivo

Jan Paul Medema1, Joan de Jong1, Sandra Bres1, Ton Schumacher2, Mireille Toebes2, Kees Melief1 and Rienk Offringa1.

1Dept. of Immunohematology and Blood transfusion, Leiden University Medical Center, Leiden, The Netherlands

2Dept. of Tumorimmunology, The Netherlands Cancer Institute, Amsterdam, The Netherlands

 

The murine protease inhibitor SPI-6 belongs to the large family of Serpin Protease Inhibitors . SPI-6 has a high specificity for the cytotoxic granule-assoaciated protease granzymeB (GrB). Expression of SPI-6 is mainly found in cytotoxic T cells (CTLs). Since CTL can efficiently lyse target cells with the use of perforin and GrB, it is thought to protect itself against its own cytotoxic potential by the expression of SPI-6. Since several tumor cells have been shown to be resistant to CTL-induced killing both in vitro and in vivo we set out to determine the underlying mechanisms that control this resistance. Previously we showed that certain tumor cells that express the apoptosis inhibitor c-FLIP become resistant to the CD95-pathway and can thereby escape from CTL-induced apoptosis in vivo. Here we show that expression of the GrB-inhibitor SPI-6 completely inhibits CTL-induced apoptosis through the perforin/GrB pathway . More importantly, northern analysis revealed that a SPI-6 homologue is expressed at very high levels in tumor cells which are resistant to CTL-induced apoptosis in vitro and in vivo. Currently we are cloning this factor and will try to characterise its function in tumor growth.

 

The role of a tumor-specific environment in the apoptotic activity of Apoptin

Jennifer L. Rohn1, Astrid Danen-van Oorshot1, 2, Patrick Voskamp1, Martine Miltenburg1 and Mathieu H. M. Noteborn1,2

1Leadd BV, and 2Leiden University Medical Center, Leiden, The Netherlands

 

Apoptin (VP3) is a chicken anemia virus-encoded protein that is able to induce apoptosis in cells in which it is expressed. The ability of Apoptin to kill exhibits a remarkable specificity; namely, transformed or tumor cells are susceptible, whereas normal cells are completely resistant. Moreover, the localization of Apoptin correlates with this tumor-specific apoptotic activity. Specifically, while Apoptin is found in the cytoplasm of normal cells, it is situated in the nucleus of tumor cells. We have hypothesized that the differential killing ability of Apoptin could result from the protein responding differently to a tumor-specific state. The nature of this state could in principle consist of a state-specific modification of Apoptin, the binding of Apoptin to a state-specific co-factor, or a combination of both. To investigate the first possibility, we examined whether Apoptin is differentially modified in tumor versus normal cells; preliminary evidence suggests that Apoptin is indeed phosphorylated in a state-dependent manner. To study the second possibility, we performed a yeast two-hybrid screen of a tumor library using full-length Apoptin as “bait”, and isolated a number of bona fide associating proteins, some of which possess clear tumor-specific phenotypes. These ongoing studies support the hypothesis that the tumor-specific apoptotic activity of Apoptin may respond to an underlying, and possibly important, fundamental difference in state between the normal and the transformed cell.

 

Session XI: Apoptosis and tumors                      Tuesday April 4th

 

Engagement of the Apoptotic Machinery in Prostate Cancer

Marco Marcelli1, Michela Marani1, Lydia Sturgis2, Joe Haidacher2, Roberta Mannucci3, Ildo Nicoletti3, and Larry Denner2.

1VA Medical Center and Baylor College Of Medicine, Houston, TX; 2Texas Biotechnology Corp., Houston,TX; 3Perugia Univ. Medical School, Perugia, Italy

 

Metastatic prostate cancer occurs when cells escape hormone ablation-induced apoptosis. Cell lines derived from different metastatic sites have varied genotypes and exhibit cell-specific and inducer-specific differences in sensitivity to engagement of the apoptotic machinery. These differences are evident based on analyses of dissipation of the mitochondrial membrane potential, regulation and localization of the Bcl-2 family members, release of cytochrome c from the mitochondria to the cytoplasm, proteolytic processing and catalytic activation of caspases, cleavage of the death substrates DFF and PARP, and expression of morphological features seen in TUNEL staining. Thus, while the LNCaP line is very sensitive to engagement of the apparatus, PC-3 cells are relatively inert to many inducers. Further, inducing agents such as staurosporin elicit different responses than viral-mediated overexpression of caspase-3, caspase–7, or Bax. In some but not all prostate cancer cell lines, the Bcl-2/Bax family mediates the apoptotic response. Regulation of engagement of these apoptotic signalling intermediates in therapeutic intervention will be discussed.

 

Molecular analysis of radiation-induced apoptosis in paraffin-embedded tumor and normal tissue of rectal cancer patients

Lucy T.C. Peltenburg1, Corrie A.M. Marijnen1, Iris D. Nagtegaal2, Adri A. Mulder-Stapel2, J. Han J.M. van Krieken3 and Peter I. Schrier1.

Departments of Clinical Oncology1 and Pathology2, Leiden University Medical Center, Leiden, Department of Pathology3, Nijmegen University Hospital, The Netherlands

 

Numerous studies of molecular factors that influence apoptosis have been done in in vitro tissue culture systems. In contrast, we have investigated the occurrence and modulation of apoptosis in human tumors that were treated with radiotherapy. We analyzed a large collection of tumor tissue samples, derived from a randomized trial on preoperative radiotherapy of rectal cancer patients. This trial included over 1400 patients, of which pre- and postoperative tumor samples are available, thus providing a unique system to investigate the role of apoptosis in vivo. Proteins were extracted from paraffin-embedded pre-treatment biopsies, tumors and normal mucosa of 50 irradiated and 50 non-irradiated patients. As a measure of apoptosis, we determined the ratio of full-length and cleaved gelsolin by Western blotting. To evaluate the reliability of this method, the numbers of apoptotic cells were also determined by immunohistochemistry using an antibody specific for the apoptosis-induced cleavage product of cytokeratin 18. By using these assays, expression of oncogenes, tumor suppressor genes and the Bcl-2 family members can as well be quantified. The methods of these analyses, as well as the differences in the level of apoptosis and correlations with apoptosis determinants in irradiated and non-irradiated tissues will be discussed.

 

Session XI: Apoptosis and tumors                     Tuesday April 4th

 

Modulation of Survivin expression by CD40L in B‑chronic lymphocytic leukemia (B‑CLL)

Luisa Granziero, Paola Circosta, Giuliana Strola, Massimo Geuna, Daniela Gottardi, Pier Carlo Marchisio, Dario Altieri, Marco Chilosi, Federico Caligaris‑Capplo and Paolo Ghia.

Istituto per la Ricerca e la Cura del Cancro, Candiolo (TO); Divisione di Immunologia Clinica, Ospedale Mauriziano Umberto 1, Dipartimento Scienze Biomediche ed Oncologia Umana, Università di Torino

 

B‑CLL is a human malignancy that primarily involves defects in apoptosis. Although the malignant cells progressively accumulate in vivo, they rapidly undergo apoptosis when cultured in vitro; supporting a role for the microenvironment. A new family of inhibitors of apoptosis proteins (IAP) has been cloned in humans and so far six different members have been recognized (cIAP1, cIAP2, NAIP, XIAP, Survivin and Apollon) that suppress apoptosis by caspase and pro‑caspase inhibition. We analyzed the expression of these genes in CD19+/CD5+ cells from peripheral blood of 10 B‑CLL patients at diagnosis and after 7 days of culture with and without the soluble form of the CD40 ligand (CD40L). The in vitro apoptosis of cells exposed to CD40L was significantly reduced. RT‑PCR analysis showed that the expression of IAPs was not modified after stimulation, with the notable exception of survivin, which was strongly up‑regulated after CD40 activation. The results were confirmed at protein level, by FACS and western blot analyses. In immunohistochemistry, malignant cells in bone marrow and lymph nodes from 6 B‑CLL patients, were highly positive for survivin while they were negative in the blood. Taken together, these observations indicate that a signal through CD40 might be responsible for the induction of an apoptosis-resistant phenotype in B‑CLL cells, mainly in secondary lymphoid tissues, suggesting a possible mechanism for the accumulation of malignant cells.

 

Protection against an non‑immanogenic melanoma by vaccination with apoptotic tumor cells coupled with TNF‑a

V.S. Zimmerman, Patrizia Rovere, A. Bondanza, F. Curnis, A. Corti, C.Rugarli, A.A. Manfredi.

Hospital San Raffaele, Laboratory of Tumor Immunology, Milano

 

Apoptotic cells are usually cleared by phagocytosis without causing inflammation. In vivo, tumors cells, which contain relevant tumor associated antigens, die by apoptosis in an environment devoid of inflammatory signals and do not induce an efficace immune response. We have shown previously that vaccination with apoptotic tumor cells induces a functional and long lasting immune response against tumor. However, this response is limited by the production of immunosoppressive cytokines including IL-10. In order to augment the efficiency of the procedure we vaccinated C57BL/6 with apoptotic B16 melanoma cells coupled covalently with the pro‑inflammatory cytokine TNF‑a. This coupling was achieved by the way of a biotin‑avidin bridge. We have verified in vitro that the TNF‑a coupled to the apoptotic tumor cells is bioactive since it induced cell death and dendritic cell maturation. In vivo, the vaccination with apoptotic B16 melanoma coupled with TNF‑a induced the priming of tumor specific CTL and protection (rejection or delay in the growth) against a further challenge with living B16.These results confirm that the cytokine environment at the site of apoptotic cell clearance determines the establishment of immune response towards intracellular antigens and provide a tool for clinical intervention.